Pharmacoresponse in genetic generalized epilepsy: a genome-wide association study

Pharmacogenomics. 2020 Apr;21(5):325-335. doi: 10.2217/pgs-2019-0179. Epub 2020 Apr 20.

Abstract

Aim: Pharmacoresistance is a major burden in epilepsy treatment. We aimed to identify genetic biomarkers in response to specific antiepileptic drugs (AEDs) in genetic generalized epilepsies (GGE). Materials & methods: We conducted a genome-wide association study (GWAS) of 3.3 million autosomal SNPs in 893 European subjects with GGE - responsive or nonresponsive to lamotrigine, levetiracetam and valproic acid. Results: Our GWAS of AED response revealed suggestive evidence for association at 29 genomic loci (p <10-5) but no significant association reflecting its limited power. The suggestive associations highlight candidate genes that are implicated in epileptogenesis and neurodevelopment. Conclusion: This first GWAS of AED response in GGE provides a comprehensive reference of SNP associations for hypothesis-driven candidate gene analyses in upcoming pharmacogenetic studies.

Keywords: GWAS; antiepileptic drugs; genetic generalized epilepsy; lamotrigine; levetiracetam; pharmacoresistance; valproic acid.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Anticonvulsants / therapeutic use*
  • Case-Control Studies
  • Child
  • Cohort Studies
  • Epilepsy, Generalized / drug therapy*
  • Epilepsy, Generalized / epidemiology
  • Epilepsy, Generalized / genetics*
  • Europe / epidemiology
  • Female
  • Genome-Wide Association Study / methods*
  • Humans
  • Lamotrigine / therapeutic use
  • Levetiracetam / therapeutic use
  • Male
  • Retrospective Studies
  • Treatment Outcome
  • Valproic Acid / therapeutic use

Substances

  • Anticonvulsants
  • Levetiracetam
  • Valproic Acid
  • Lamotrigine