Genetic Susceptibility to Systemic Sclerosis in the Greek-Cypriot Population: A Pilot Study

Genet Test Mol Biomarkers. 2020 May;24(5):309-317. doi: 10.1089/gtmb.2019.0255. Epub 2020 Apr 21.

Abstract

Background: Systemic Sclerosis (SSc), also known as scleroderma, is an autoimmune rheumatic disease, which is clinically subdivided into two major subgroups; limited (lcSSc) and diffuse cutaneous scleroderma (dcSSc). Even though the SSc etiologies remains unclear, some HLA and non-HLA genetic variants have been associated with the disease. Aim: This study was designed to evaluate the associations between several HLA-related genetic variants and SSc in the Greek-Cypriot population. Methods: Forty-one SSc patients and 164 controls were genotyped at 18 selected single nucleotide polymorphisms (SNPs) using restriction fragment length polymorphism analyses, Sanger sequencing, and a multiplex SNaPshot minisequencing assay. Logistic regression analysis under the log-additive model was used to evaluate all possible associations between these SNPs and SSc; nominal statistical significance was assumed at p < 0.05. Results: Associations of SSc with SNPs rs3117230, rs3128930, and rs3128965 within the HLA-DPB1 and HLA-DPB2 regions were observed in the Greek-Cypriot population at the level of p < 0.05. However, none of these associations survived a Bonferroni correction. The direction of the effect is consistent with the direction reported in previous studies. In addition, allele frequencies of the majority of the selected SNPs in the Greek-Cypriot population are similar to those reported in the European population. Conclusion: This study initiates the genetic investigation of SSc in the Greek-Cypriot population, a relatively small newly investigated population. Further investigation with a larger sample size and/or additional SSc susceptibility loci may confirm the association of some of these variants with SSc in the Greek-Cypriot population that could potentially be used for predictive testing.

Keywords: autoimmunity; population study; susceptibility loci; systemic sclerosis.

MeSH terms

  • Adult
  • Alleles
  • Case-Control Studies
  • Cyprus / epidemiology
  • Female
  • Gene Frequency / genetics
  • Genetic Predisposition to Disease / genetics
  • Genotype
  • Greece / epidemiology
  • HLA-DP beta-Chains / genetics
  • HLA-DP beta-Chains / immunology
  • Histocompatibility Antigens Class I / genetics*
  • Histocompatibility Antigens Class I / immunology
  • Histocompatibility Antigens Class II / genetics*
  • Histocompatibility Antigens Class II / immunology
  • Humans
  • Male
  • Middle Aged
  • Phenotype
  • Pilot Projects
  • Polymorphism, Single Nucleotide / genetics
  • Scleroderma, Systemic / genetics*
  • Scleroderma, Systemic / metabolism

Substances

  • HLA-DP beta-Chains
  • HLA-DPB1 antigen
  • Histocompatibility Antigens Class I
  • Histocompatibility Antigens Class II