Autoimmune Encephalitis in Children: A Case Series at a Tertiary Care Center

J Child Neurol. 2020 Aug;35(9):591-599. doi: 10.1177/0883073820923834. Epub 2020 May 27.

Abstract

Autoimmune encephalitis is the third most common cause of encephalitis in children. We provide a detailed account of presenting symptoms, diagnosis, and response to treatment in pediatric autoimmune encephalitis patients evaluated at University of California San Francisco within a 2.5-year period. Eleven were identified: anti-N-methyl-d-aspartate receptor (NMDAR) encephalitis (n = 4), antibody-negative autoimmune encephalitis (n = 4), steroid-responsive encephalopathy associated with thyroiditis (SREAT) (n = 2), and glial fibrillary acidic protein (GFAP)-associated encephalitis (n = 1). Most common presenting symptoms included seizures and behavior changes (54%). More than 90% of patients showed improvement following first-line immunotherapy (high-dose corticosteroids, intravenous immunoglobulin, and/or plasma exchange). A total of 64% received second-line treatment with rituximab, cyclophosphamide, or mycophenolate mofetil. One patient with NMDAR encephalitis died despite escalating immunotherapy. None of the patients showed complete recovery after median follow-up of 9 months (range 0.5-66). Children with autoimmune encephalitis have a diverse clinical presentation and may lack an identifiable autoantibody. Majority of patients show a good response to immunotherapy; however, recovery can be delayed.

Keywords: autoimmune encephalitis; children; neuroinflammation.

MeSH terms

  • Adolescent
  • Antineoplastic Agents, Immunological / therapeutic use
  • Autoimmune Diseases / diagnosis*
  • Autoimmune Diseases / drug therapy*
  • Autoimmune Diseases / pathology
  • Child
  • Child, Preschool
  • Encephalitis / diagnosis*
  • Encephalitis / drug therapy*
  • Encephalitis / pathology
  • Female
  • Humans
  • Immunoglobulins, Intravenous / therapeutic use
  • Immunologic Factors / therapeutic use
  • Immunotherapy / methods*
  • Infant
  • Male
  • Retrospective Studies
  • Tertiary Care Centers

Substances

  • Antineoplastic Agents, Immunological
  • Immunoglobulins, Intravenous
  • Immunologic Factors