Genetic variant of SRF-rearranged myofibroma with a misleading nuclear expression of STAT6 and STAT6 involvement as 3' fusion partner

Virchows Arch. 2021 Mar;478(3):597-603. doi: 10.1007/s00428-020-02859-9. Epub 2020 Jun 11.

Abstract

Pediatric neoplasms with a myofibroblastic differentiation are frequent in children, in particular myofibroma. Recently, a novel deep soft tissue myofibroblastic neoplasm has been described with high cellularity, a smooth muscle phenotype and SRF-RELA fusion. We report the case of a 15-year-old boy who presented with a tumor of the deep soft tissue of the arm, with overlapping histological features with the recently described SRF-RELA group of myofibromas but differing by the presence of calcifications, a novel SRF-STAT6 fusion transcript and nuclear expression of STAT6. No local recurrence nor distant metastasis was detected at the current follow-up of 29 months. The clinical relevance of this novel fusion requires further investigations.

Keywords: Leiomyoma; Myofibroblastic proliferation; Myofibroma; Myopericytoma; Pediatric; RELA; SRF; STAT6; Smooth muscle neoplasm.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Biomarkers, Tumor / analysis
  • Biomarkers, Tumor / genetics*
  • Cell Nucleus / chemistry
  • Cell Nucleus / genetics*
  • Cell Nucleus / pathology
  • Gene Fusion*
  • Gene Rearrangement*
  • Humans
  • Immunohistochemistry
  • Male
  • Myofibroma / chemistry
  • Myofibroma / diagnostic imaging
  • Myofibroma / genetics*
  • Myofibroma / pathology
  • STAT6 Transcription Factor / analysis
  • STAT6 Transcription Factor / genetics*
  • Sequence Analysis, RNA
  • Serum Response Factor / genetics*
  • Soft Tissue Neoplasms / chemistry
  • Soft Tissue Neoplasms / diagnostic imaging
  • Soft Tissue Neoplasms / genetics*
  • Soft Tissue Neoplasms / pathology
  • Upper Extremity

Substances

  • Biomarkers, Tumor
  • SRF protein, human
  • STAT6 Transcription Factor
  • STAT6 protein, human
  • Serum Response Factor