Propranolol syrup to tablets change triggers electrical storm in Jervell-Lange-Nielsen syndrome

Cardiol Young. 2021 Jan;31(1):141-143. doi: 10.1017/S1047951120003285. Epub 2020 Oct 13.

Abstract

A 10-year-old girl with genetically confirmed Jervell-Lange-Nielsen syndrome treated with beta-blocker and developed electrical storm after changing propranolol syrup to tablets. Jervell-Lange-Nielsen is characterised by long QT and congenital sensorineural deafness, with high risk of malignant arrhythmias at early ages. Gastric involvement and achlorhydria may be present, with subsequent alteration of medication bioavailability which can trigger severe arrhythmic complications.

Keywords: Jervell-Lange-Nielsen syndrome; bioavailability; electrical storm; long QT interval; thoracic sympathectomy.

Publication types

  • Case Reports

MeSH terms

  • Adrenergic beta-Antagonists
  • Arrhythmias, Cardiac / drug therapy
  • Child
  • Female
  • Humans
  • Jervell-Lange Nielsen Syndrome* / diagnosis
  • Jervell-Lange Nielsen Syndrome* / drug therapy
  • Long QT Syndrome* / chemically induced
  • Long QT Syndrome* / diagnosis
  • Propranolol
  • Tablets

Substances

  • Adrenergic beta-Antagonists
  • Tablets
  • Propranolol