An Unusual Pattern of Premature Cervical Spine Degeneration in STAT3-LOF

J Clin Immunol. 2021 Apr;41(3):576-584. doi: 10.1007/s10875-020-00926-z. Epub 2021 Jan 6.

Abstract

Loss of function mutations in STAT3 (STAT3-LOF; autosomal dominant hyper-IgE (Job's) syndrome) are associated with a variety of musculoskeletal manifestations, including scoliosis, osteoporosis, and minimal trauma fractures. This retrospective magnetic resonance (MR) imaging study sought to characterize an unusual pattern of cervical spine degeneration among a cohort of STAT3-LOF patients. Cervical spine MR images of the STAT3-LOF cohort (n = 38) were assessed for a variety of degenerative changes and compared to age-matched groups of controls (n = 42) without known immune or musculoskeletal abnormalities. A unique pattern of premature cervical spine degeneration was identified among the STAT3-LOF cohort which included straightening and eventual reversal of the normal cervical lordosis, mainly due to multi-level spondylolisthesis, as well as early development of spinal canal narrowing, cord compression, and myelomalacia. Cervical spine degeneration in the STAT3-LOF cohort was significantly worse than controls in both the 30-45 and 45 + age groups. Moderate to severe degenerative changes were present after age 30, and markedly worsened over time in several cases. Bone mineral density (BMD) had a moderate negative correlation with cervical degeneration severity and a strong negative correlation with age among STAT3-LOF participants. Cervical degeneration in STAT3-LOF appears to be progressive and could result in cord compromise if left unaddressed. Focused history and physical examination for signs of neurologic compromise as well as periodic MR imaging are thus recommended for the evaluation of premature cervical spine degeneration in STAT3-LOF patients after age 30 so that timely surgical interventions may be considered to prevent spinal cord damage and permanent neurological deficits.

Keywords: Cervical spine degeneration; Magnetic resonance imaging; Primary immunodeficiency; STAT3-LOF.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, N.I.H., Intramural

MeSH terms

  • Adolescent
  • Adult
  • Bone Density
  • Cervical Vertebrae / pathology*
  • Female
  • Genetic Association Studies
  • Genetic Predisposition to Disease
  • Humans
  • Loss of Function Mutation / genetics*
  • Magnetic Resonance Imaging
  • Male
  • Middle Aged
  • STAT3 Transcription Factor / genetics*
  • Scoliosis / diagnosis
  • Scoliosis / etiology
  • Severity of Illness Index
  • Spinal Diseases / diagnosis*
  • Spinal Diseases / etiology*
  • Young Adult

Substances

  • STAT3 Transcription Factor
  • STAT3 protein, human