C. elegans orthologs MUT-7/CeWRN-1 of Werner syndrome protein regulate neuronal plasticity

Elife. 2021 Mar 1:10:e62449. doi: 10.7554/eLife.62449.

Abstract

Caenorhabditis elegans expresses human Werner syndrome protein (WRN) orthologs as two distinct proteins: MUT-7, with a 3'-5' exonuclease domain, and CeWRN-1, with helicase domains. How these domains cooperate remains unclear. Here, we demonstrate the different contributions of MUT-7 and CeWRN-1 to 22G small interfering RNA (siRNA) synthesis and the plasticity of neuronal signaling. MUT-7 acts specifically in the cytoplasm to promote siRNA biogenesis and in the nucleus to associate with CeWRN-1. The import of siRNA by the nuclear Argonaute NRDE-3 promotes the loading of the heterochromatin-binding protein HP1 homolog HPL-2 onto specific loci. This heterochromatin complex represses the gene expression of the guanylyl cyclase ODR-1 to direct olfactory plasticity in C. elegans. Our findings suggest that the exonuclease and helicase domains of human WRN may act in concert to promote RNA-dependent loading into a heterochromatin complex, and the failure of this entire process reduces plasticity in postmitotic neurons.

Keywords: 22G small RNA; 3'-5' exonuclease; C. elegans; neuronal plasticity; neuroscience; werner syndrome protein.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Caenorhabditis elegans / genetics
  • Caenorhabditis elegans Proteins / metabolism
  • DNA Helicases / genetics
  • DNA Helicases / metabolism*
  • Exonucleases
  • Heterochromatin
  • Neuronal Plasticity
  • RNA, Small Interfering / metabolism
  • Werner Syndrome / genetics
  • Werner Syndrome / metabolism*
  • Werner Syndrome Helicase / genetics
  • Werner Syndrome Helicase / metabolism*

Substances

  • Caenorhabditis elegans Proteins
  • Heterochromatin
  • RNA, Small Interfering
  • Exonucleases
  • DNA Helicases
  • Werner Syndrome Helicase