Gene Therapies for Primary Immune Deficiencies

Front Immunol. 2021 Feb 25:12:648951. doi: 10.3389/fimmu.2021.648951. eCollection 2021.

Abstract

Gene therapy is an innovative treatment for Primary Immune Deficiencies (PIDs) that uses autologous hematopoietic stem cell transplantation to deliver stem cells with added or edited versions of the missing or malfunctioning gene that causes the PID. Initial studies of gene therapy for PIDs in the 1990-2000's used integrating murine gamma-retroviral vectors. While these studies showed clinical efficacy in many cases, especially with the administration of marrow cytoreductive conditioning before cell re-infusion, these vectors caused genotoxicity and development of leukoproliferative disorders in several patients. More recent studies used lentiviral vectors in which the enhancer elements of the long terminal repeats self-inactivate during reverse transcription ("SIN" vectors). These SIN vectors have excellent safety profiles and have not been reported to cause any clinically significant genotoxicity. Gene therapy has successfully treated several PIDs including Adenosine Deaminase Severe Combined Immunodeficiency (SCID), X-linked SCID, Artemis SCID, Wiskott-Aldrich Syndrome, X-linked Chronic Granulomatous Disease and Leukocyte Adhesion Deficiency-I. In all, gene therapy for PIDs has progressed over the recent decades to be equal or better than allogeneic HSCT in terms of efficacy and safety. Further improvements in methods should lead to more consistent and reliable efficacy from gene therapy for a growing list of PIDs.

Keywords: gene therapy; hematopoietic stem cell; lentiviral vector; primary immune deficiency; retroviral vector.

Publication types

  • Review

MeSH terms

  • Genetic Therapy / methods*
  • Genetic Therapy / trends
  • Granulomatous Disease, Chronic / genetics
  • Granulomatous Disease, Chronic / therapy
  • Hematopoietic Stem Cell Transplantation / methods*
  • Hematopoietic Stem Cells / cytology
  • Hematopoietic Stem Cells / metabolism*
  • Humans
  • Primary Immunodeficiency Diseases / genetics
  • Primary Immunodeficiency Diseases / therapy*
  • Severe Combined Immunodeficiency / genetics
  • Severe Combined Immunodeficiency / therapy
  • Treatment Outcome
  • Wiskott-Aldrich Syndrome / genetics
  • Wiskott-Aldrich Syndrome / therapy
  • X-Linked Combined Immunodeficiency Diseases / genetics
  • X-Linked Combined Immunodeficiency Diseases / therapy