Identification of a Novel FUS/ETV4 Fusion and Comparative Analysis with Other Ewing Sarcoma Fusion Proteins

Mol Cancer Res. 2021 Nov;19(11):1795-1801. doi: 10.1158/1541-7786.MCR-21-0354. Epub 2021 Aug 31.

Abstract

Ewing sarcoma is a pediatric bone cancer defined by a chromosomal translocation fusing one of the FET family members to an ETS transcription factor. There have been seven reported chromosomal translocations, with the most recent reported over a decade ago. We now report a novel FET/ETS translocation involving FUS and ETV4 detected in a patient with Ewing sarcoma. Here, we characterized FUS/ETV4 by performing genomic localization and transcriptional regulatory studies on numerous FET/ETS fusions in a Ewing sarcoma cellular model. Through this comparative analysis, we demonstrate significant similarities across these fusions, and in doing so, validate FUS/ETV4 as a bona fide Ewing sarcoma translocation. This study presents the first genomic comparison of Ewing sarcoma-associated translocations and reveals that the FET/ETS fusions share highly similar, but not identical, genomic localization and transcriptional regulation patterns. These data strengthen the notion that FET/ETS fusions are key drivers of, and thus pathognomonic for, Ewing sarcoma. IMPLICATIONS: Identification and initial characterization of the novel Ewing sarcoma fusion, FUS/ETV4, expands the family of Ewing fusions and extends the diagnostic possibilities for this aggressive tumor of adolescents and young adults.

Publication types

  • Case Reports
  • Research Support, N.I.H., Extramural

MeSH terms

  • Humans
  • Infant, Newborn
  • Oncogene Proteins, Fusion / genetics
  • Proto-Oncogene Proteins c-ets / metabolism*
  • RNA-Binding Protein FUS / metabolism*
  • Sarcoma, Ewing / genetics*
  • Sarcoma, Ewing / pathology
  • Translocation, Genetic / genetics*

Substances

  • ETV4 protein, human
  • FUS protein, human
  • Oncogene Proteins, Fusion
  • Proto-Oncogene Proteins c-ets
  • RNA-Binding Protein FUS