[Genetic testing and prenatal diagnosis for a Chinese pedigree affected with mitochondrial DNA depletion syndrome due to variant of MPV17 gene]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2022 Oct 10;39(10):1085-1088. doi: 10.3760/cma.j.cn511374-20210718-00604.
[Article in Chinese]

Abstract

Objective: To explore the genetic etiology of a Chinese pedigree affected with infantile hepatitis syndrome.

Methods: Genes associated with liver diseases subjected to high-throughput sequencing. Candidate variants were validated by Sanger sequencing of the proband and his parents. The pathogenicity of the variants was analyzed through bioinformatic analysis.

Results: High-throughput sequencing revealed that the proband has harbored c.182T>C (p.F61S) and c.293C>T (p.P98L) variants of the MPV17 gene, which were verified by Sanger sequencing to be inherited from his parents. The variant c.182T>C (p.F61S) was unreported previously and predicted to be likely pathogenic by bioinformatic analysis.

Conclusion: The proband was caused by the compound heterozygous variations of MPV17 gene including c.182T>C (p.F61S) and c.293C>T (p.P98L). Discovery of the novel variant has enriched the spectrum of pathogenic variants of the MPV17 gene.

MeSH terms

  • China
  • DNA, Mitochondrial / genetics
  • Female
  • Genetic Testing*
  • Humans
  • Membrane Proteins / genetics
  • Metabolism, Inborn Errors* / genetics
  • Mitochondrial Proteins / genetics
  • Mutation
  • Pedigree
  • Pregnancy
  • Prenatal Diagnosis
  • Syndrome

Substances

  • DNA, Mitochondrial
  • MPV17 protein, human
  • Membrane Proteins
  • Mitochondrial Proteins