TNIP1 inhibits selective autophagy via bipartite interaction with LC3/GABARAP and TAX1BP1

Mol Cell. 2023 Mar 16;83(6):927-941.e8. doi: 10.1016/j.molcel.2023.02.023. Epub 2023 Mar 9.

Abstract

Mitophagy is a form of selective autophagy that disposes of superfluous and potentially damage-inducing organelles in a tightly controlled manner. While the machinery involved in mitophagy induction is well known, the regulation of the components is less clear. Here, we demonstrate that TNIP1 knockout in HeLa cells accelerates mitophagy rates and that ectopic TNIP1 negatively regulates the rate of mitophagy. These functions of TNIP1 depend on an evolutionarily conserved LIR motif as well as an AHD3 domain, which are required for binding to the LC3/GABARAP family of proteins and the autophagy receptor TAX1BP1, respectively. We further show that phosphorylation appears to regulate its association with the ULK1 complex member FIP200, allowing TNIP1 to compete with autophagy receptors, which provides a molecular rationale for its inhibitory function during mitophagy. Taken together, our findings describe TNIP1 as a negative regulator of mitophagy that acts at the early steps of autophagosome biogenesis.

Keywords: FIP200; FIR; LIR; Selective autophagy; TAX1BP1; TBK1; TNIP1; mitophagy; mitophagy regulation.

Publication types

  • Research Support, Non-U.S. Gov't
  • Research Support, N.I.H., Intramural

MeSH terms

  • Apoptosis Regulatory Proteins / genetics
  • Apoptosis Regulatory Proteins / metabolism
  • Autophagy* / genetics
  • Autophagy-Related Protein 8 Family / metabolism
  • Autophagy-Related Proteins*
  • DNA-Binding Proteins / metabolism
  • HeLa Cells
  • Humans
  • Intracellular Signaling Peptides and Proteins / genetics
  • Intracellular Signaling Peptides and Proteins / metabolism
  • Mitophagy* / genetics
  • Neoplasm Proteins / metabolism

Substances

  • Apoptosis Regulatory Proteins
  • Autophagy-Related Protein 8 Family
  • DNA-Binding Proteins
  • GABARAP protein, human
  • Intracellular Signaling Peptides and Proteins
  • Neoplasm Proteins
  • TAX1BP1 protein, human
  • TNIP1 protein, human
  • Autophagy-Related Proteins