Nodal flow transfers polycystin to determine mouse left-right asymmetry

Dev Cell. 2023 Aug 21;58(16):1447-1461.e6. doi: 10.1016/j.devcel.2023.06.002. Epub 2023 Jul 5.

Abstract

Left-dominant [Ca2+]i elevation on the left margin of the ventral node furnishes the initial laterality of mouse embryos. It depends on extracellular leftward fluid flow (nodal flow), fibroblast growth factor receptor (FGFR)/sonic hedgehog (Shh) signaling, and the PKD1L1 polycystin subunit, of which interrelationship is still elusive. Here, we show that leftward nodal flow directs PKD1L1-containing fibrous strands and facilitates Nodal-mediated [Ca2+]i elevation on the left margin. We generate KikGR-PKD1L1 knockin mice in order to monitor protein dynamics with a photoconvertible fluorescence protein tag. By imaging those embryos, we have identified fragile meshwork being gradually transferred leftward involving pleiomorphic extracellular events. A portion of the meshwork finally bridges over the left nodal crown cells in an FGFR/Shh-dependent manner. As PKD1L1 N-term is predominantly associated with Nodal on the left margin and that PKD1L1/PKD2 overexpression significantly augments cellular Nodal sensitivity, we propose that leftward transfer of polycystin-containing fibrous strands determines left-right asymmetry in developing embryos.

Keywords: Ca elevation; Nodal; PKD1L1; extracellular meshwork; left-right determination; polycystin.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Body Patterning
  • Cilia / metabolism
  • Gene Expression Regulation, Developmental
  • Hedgehog Proteins* / metabolism
  • Mice
  • Nodal Protein / metabolism
  • Signal Transduction
  • TRPP Cation Channels* / genetics
  • TRPP Cation Channels* / metabolism
  • Transforming Growth Factor beta / metabolism

Substances

  • Hedgehog Proteins
  • TRPP Cation Channels
  • Transforming Growth Factor beta
  • Nodal Protein