Generation and application of endogenously floxed alleles for cell-specific knockout in zebrafish

Dev Cell. 2023 Nov 20;58(22):2614-2626.e7. doi: 10.1016/j.devcel.2023.07.022. Epub 2023 Aug 25.

Abstract

The zebrafish is amenable to a variety of genetic approaches. However, lack of conditional deletion alleles limits stage- or cell-specific gene knockout. Here, we applied an existing protocol to establish a floxed allele for gata2a but failed to do so due to off-target integration and incomplete knockin. To address these problems, we applied simultaneous co-targeting with Cas12a to insert loxP sites in cis, together with transgenic counterscreening and comprehensive molecular analysis, to identify off-target insertions and confirm targeted knockins. We subsequently used our approach to establish endogenously floxed alleles of foxc1a, rasa1a, and ruvbl1, each in a single generation. We demonstrate the utility of these alleles by verifying Cre-dependent deletion, which yielded expected phenotypes in each case. Finally, we used the floxed gata2a allele to demonstrate an endothelial autonomous requirement in lymphatic valve development. Together, our results provide a framework for routine generation and application of endogenously floxed alleles in zebrafish.

Keywords: Cre/lox; conditional genetics; foxc1a; gata2a; rasa1a; ruvbl1; zebrafish.

MeSH terms

  • Alleles
  • Animals
  • Gene Knockout Techniques
  • Integrases* / genetics
  • Mice
  • Mice, Knockout
  • Zebrafish* / genetics

Substances

  • Integrases