An α-chain modification rivals the effect of fetal hemoglobin in retarding the rate of sickle cell fiber formation

Sci Rep. 2023 Dec 11;13(1):21997. doi: 10.1038/s41598-023-48919-3.

Abstract

Adults with sickle cell disease bear a mutation in the β-globin gene, leading to the expression of sickle hemoglobin (HbS; α2βS2). Adults also possess the gene for γ-globin, which is a component of fetal hemoglobin (HbF, α2γ2); however, γ-chain expression normally ceases after birth. As HbF does not form the fibers that cause the disease, pharmacological and gene-modifying interventions have attempted to either reactivate expression of the γ chain or introduce a gene encoding a modified β chain having γ-like character. Here, we show that a single-site modification on the α chain, αPro114Arg, retards fiber formation as effectively as HbF. Because this addition to the repertoire of anti-sickling approaches acts independently of other modifications, it could be coupled with other therapies to significantly enhance their effectiveness.

MeSH terms

  • Adult
  • Anemia, Sickle Cell* / drug therapy
  • Anemia, Sickle Cell* / genetics
  • Fetal Hemoglobin* / metabolism
  • Hemoglobin, Sickle / genetics
  • Humans
  • gamma-Globins / genetics
  • gamma-Globins / metabolism

Substances

  • Fetal Hemoglobin
  • gamma-Globins
  • Hemoglobin, Sickle