VCP/p97 mediates nuclear targeting of non-ER-imported prion protein to maintain proteostasis

Life Sci Alliance. 2024 Apr 3;7(6):e202302456. doi: 10.26508/lsa.202302456. Print 2024 Jun.

Abstract

Mistargeting of secretory proteins in the cytosol can trigger their aggregation and subsequent proteostasis decline. We have identified a VCP/p97-dependent pathway that directs non-ER-imported prion protein (PrP) into the nucleus to prevent the formation of toxic aggregates in the cytosol. Upon impaired translocation into the ER, PrP interacts with VCP/p97, which facilitates nuclear import mediated by importin-ß. Notably, the cytosolic interaction of PrP with VCP/p97 and its nuclear import are independent of ubiquitination. In vitro experiments revealed that VCP/p97 binds non-ubiquitinated PrP and prevents its aggregation. Inhibiting binding of PrP to VCP/p97, or transient proteotoxic stress, promotes the formation of self-perpetuating and partially proteinase resistant PrP aggregates in the cytosol, which compromised cellular proteostasis and disrupted further nuclear targeting of PrP. In the nucleus, RNAs keep PrP in a soluble and non-toxic conformation. Our study revealed a novel ubiquitin-independent role of VCP/p97 in the nuclear targeting of non-imported secretory proteins and highlights the impact of the chemical milieu in triggering protein misfolding.

MeSH terms

  • Adenosine Triphosphatases / metabolism
  • Prion Proteins* / metabolism
  • Prions* / metabolism
  • Proteostasis
  • Ubiquitin / metabolism
  • Valosin Containing Protein / metabolism

Substances

  • Prion Proteins
  • Valosin Containing Protein
  • Adenosine Triphosphatases
  • Ubiquitin
  • Prions