Prevention of axonal loss after immediate dosage titration of immunoglobulin in multifocal motor neuropathy

Eur J Neurol. 2024 Jul;31(7):e16305. doi: 10.1111/ene.16305. Epub 2024 Apr 23.

Abstract

Background: To evaluate whether ongoing axonal loss can be prevented in multifocal motor neuropathy (MMN) treated with immunoglobulin G (IgG), a group of patients with a median disease duration of 15.7 years (range: 8.3-37.8), treated with titrated dosages of immunoglobulins, was studied electrophysiologically at time of diagnosis and at follow-up.

Results: At follow-up, the Z-score of the compound motor action potential amplitude of the median, fibular, and tibial nerves and the neurological performances were determined. In seven patients with a treatment-free period of 0.3 years (0.2-0.4), there was no progression of axonal loss (p = 0.2), whereas a trend toward further axonal loss by 1.3 Z-scores (0.9-17.0, p = 0.06) was observed in five patients with a treatment-free period of 4.0 years (0.9-9.0). The axonal loss in the group with a short treatment delay was significantly smaller than in the group with a longer treatment delay (p = 0.02). Also, there was an association between treatment delay and ongoing axonal loss (p = 0.004). The electrophysiological findings at follow-up were associated with the isokinetic strength performance, the neurological impairment score, and the disability, supporting the clinical relevance of the electrophysiological estimate of axonal loss.

Conclusion: Swift initiation of an immediately titrated IgG dosage can prevent further axonal loss and disability in continuously treated MMN patients.

Keywords: inflammatory neuropathy; multifocal motor neuropathy; neurological disorders; neuromuscular diseases.

MeSH terms

  • Action Potentials / drug effects
  • Action Potentials / physiology
  • Adult
  • Aged
  • Axons* / drug effects
  • Axons* / pathology
  • Female
  • Follow-Up Studies
  • Humans
  • Immunoglobulin G / administration & dosage
  • Immunoglobulins, Intravenous / administration & dosage
  • Immunoglobulins, Intravenous / therapeutic use
  • Male
  • Middle Aged
  • Motor Neuron Disease / drug therapy
  • Neural Conduction / drug effects
  • Neural Conduction / physiology
  • Polyneuropathies* / drug therapy

Substances

  • Immunoglobulin G
  • Immunoglobulins, Intravenous