Valosin-Containing Protein (VCP)/p97 Oligomerization

Subcell Biochem. 2024:104:485-501. doi: 10.1007/978-3-031-58843-3_18.

Abstract

Valosin-containing protein (VCP), also known as p97, is an evolutionarily conserved AAA+ ATPase essential for cellular homeostasis. Cooperating with different sets of cofactors, VCP is involved in multiple cellular processes through either the ubiquitin-proteasome system (UPS) or the autophagy/lysosomal route. Pathogenic mutations frequently found at the interface between the NTD domain and D1 ATPase domain have been shown to cause malfunction of VCP, leading to degenerative disorders including the inclusion body myopathy associated with Paget disease of bone and frontotemporal dementia (IBMPFD), amyotrophic lateral sclerosis (ALS), and cancers. Therefore, VCP has been considered as a potential therapeutic target for neurodegeneration and cancer. Most of previous studies found VCP predominantly exists and functions as a hexamer, which unfolds and extracts ubiquitinated substrates from protein complexes for degradation. However, recent studies have characterized a new VCP dodecameric state and revealed a controlling mechanism of VCP oligomeric states mediated by the D2 domain nucleotide occupancy. Here, we summarize our recent knowledge on VCP oligomerization, regulation, and potential implications of VCP in cellular function and pathogenic progression.

Keywords: ALS; Cancer; Dodecamer; Hexamer; IBMPFD; Nucleotide binding; Oligomerization; Ubiquitination; VCP/p97.

Publication types

  • Review

MeSH terms

  • Adenosine Triphosphatases / chemistry
  • Adenosine Triphosphatases / genetics
  • Adenosine Triphosphatases / metabolism
  • Animals
  • Cell Cycle Proteins / chemistry
  • Cell Cycle Proteins / genetics
  • Cell Cycle Proteins / metabolism
  • Frontotemporal Dementia / genetics
  • Frontotemporal Dementia / metabolism
  • Humans
  • Muscular Dystrophies, Limb-Girdle
  • Mutation
  • Myositis, Inclusion Body / genetics
  • Myositis, Inclusion Body / metabolism
  • Osteitis Deformans / genetics
  • Osteitis Deformans / metabolism
  • Protein Multimerization
  • Valosin Containing Protein* / chemistry
  • Valosin Containing Protein* / genetics
  • Valosin Containing Protein* / metabolism

Substances

  • Valosin Containing Protein
  • VCP protein, human
  • Adenosine Triphosphatases
  • Cell Cycle Proteins

Supplementary concepts

  • Inclusion Body Myopathy With Early-Onset Paget Disease And Frontotemporal Dementia