Synergistic effects of combined BET and FAK inhibition against Vestibular Schwannomas in NF2-related Schwannomatosis

Oncogene. 2024 Sep;43(40):2995-3002. doi: 10.1038/s41388-024-03144-8. Epub 2024 Aug 29.

Abstract

Neurofibromatosis type 2 (NF2) is a rare disorder that causes vestibular schwannomas (VS), meningiomas and ependymomas. To date, there is no FDA approved drug-based treatment for NF2. We have previously identified that BET inhibition can selectively reduce growth of the NF2-null schwannoma and Schwann cells in vitro and tumorigenesis in vivo and, separately, reported that inhibition of Focal Adhesion Kinase 1 (FAK1) via crizotinib has antiproliferative effects in NF2-null Schwann cells. The current study was aimed at determining whether combined BET and FAK inhibition can synergize and to identify the mechanisms of action. A panel of normal and NF2-null Schwann and schwannoma cell lines were used to characterize the effects of combined BET and FAK inhibition in vitro and in vivo using pharmacological and genetic approaches. The mechanism of action was explored by chromatin immunoprecipitation, ChIP-PCR, western blotting, and functional approaches. We find that combined BET and FAK inhibition are synergistic and inhibit the proliferation of NF2-null schwannoma and Schwann cell lines in vitro and in vivo, by arresting cells in the G1/S and G2/M phases of the cell cycle. Further, we identify the mechanism of action through the downregulation of FAK1 transcription by BET inhibition, which potentiates inhibition of FAK by 100-fold. Our findings suggest that combined targeting of BET and FAK1 may offer a potential therapeutic option for the treatment of NF2-related schwannomas.

MeSH terms

  • Animals
  • Cell Line, Tumor
  • Cell Proliferation* / drug effects
  • Drug Synergism
  • Focal Adhesion Kinase 1* / antagonists & inhibitors
  • Focal Adhesion Kinase 1* / genetics
  • Focal Adhesion Kinase 1* / metabolism
  • Humans
  • Mice
  • Neurilemmoma* / drug therapy
  • Neurilemmoma* / genetics
  • Neurilemmoma* / metabolism
  • Neurilemmoma* / pathology
  • Neurofibromatoses / drug therapy
  • Neurofibromatoses / genetics
  • Neurofibromatoses / pathology
  • Neurofibromatosis 2 / drug therapy
  • Neurofibromatosis 2 / genetics
  • Neurofibromatosis 2 / metabolism
  • Neurofibromatosis 2 / pathology
  • Neurofibromin 2* / genetics
  • Neurofibromin 2* / metabolism
  • Neuroma, Acoustic* / drug therapy
  • Neuroma, Acoustic* / genetics
  • Neuroma, Acoustic* / metabolism
  • Neuroma, Acoustic* / pathology
  • Schwann Cells / drug effects
  • Schwann Cells / metabolism
  • Schwann Cells / pathology
  • Skin Neoplasms / drug therapy
  • Skin Neoplasms / genetics
  • Skin Neoplasms / metabolism
  • Skin Neoplasms / pathology
  • Xenograft Model Antitumor Assays

Substances

  • Focal Adhesion Kinase 1
  • Neurofibromin 2
  • PTK2 protein, human
  • NF2 protein, human

Supplementary concepts

  • Schwannomatosis