Differentiating visceral sensory ganglion organoids from induced pluripotent stem cells

Nat Methods. 2024 Nov;21(11):2135-2146. doi: 10.1038/s41592-024-02455-8. Epub 2024 Oct 22.

Abstract

The ability to generate visceral sensory neurons (VSN) from induced pluripotent stem (iPS) cells may help to gain insights into how the gut-nerve-brain axis is involved in neurological disorders. We established a protocol to differentiate human iPS-cell-derived visceral sensory ganglion organoids (VSGOs). VSGOs exhibit canonical VSN markers, and single-cell RNA sequencing revealed heterogenous molecular signatures and developmental trajectories of VSGOs aligned with native VSN. We integrated VSGOs with human colon organoids on a microfluidic device and applied this axis-on-a-chip model to Alzheimer's disease. Our results suggest that VSN could be a potential mediator for propagating gut-derived amyloid and tau to the brain in an APOE4- and LRP1-dependent manner. Furthermore, our approach was extended to include patient-derived iPS cells, which demonstrated a strong correlation with clinical data.

MeSH terms

  • Alzheimer Disease / metabolism
  • Alzheimer Disease / pathology
  • Cell Differentiation*
  • Ganglia, Sensory / cytology
  • Ganglia, Sensory / metabolism
  • Humans
  • Induced Pluripotent Stem Cells* / cytology
  • Induced Pluripotent Stem Cells* / metabolism
  • Lab-On-A-Chip Devices
  • Organoids* / cytology
  • Organoids* / metabolism
  • Sensory Receptor Cells / cytology
  • Sensory Receptor Cells / metabolism
  • Sensory Receptor Cells / physiology