Postzygotic instability of the myotonic dystrophy p[AGC] in repeat supported by larger expansions in muscle and reduced amplifications in sperm

J Neurol. 1995 Jun;242(6):379-83. doi: 10.1007/BF00868393.

Abstract

We have analysed the [AGC] expansion in leucocytes, muscle and sperm from 17 individuals affected by myotonic dystrophy (DM). Skeletal muscle showed a larger repeat number than leucocytes in the same patient. A similar degree of expansion was detected in differently affected muscles of a single patient. The germline mutation (< or = 350 repeats) was expanded in somatic cells of the progeny in all patients examined. Our results provide evidence of an early postzygotic instability of the [AGC] repeat in DM.

Publication types

  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Child
  • Female
  • Gene Amplification
  • Humans
  • Leukocytes / physiology*
  • Male
  • Middle Aged
  • Muscle, Skeletal / physiology*
  • Myotonic Dystrophy / genetics*
  • Repetitive Sequences, Nucleic Acid*
  • Spermatozoa / physiology*
  • Zygote / physiology*