Genomic imprinting of Mash2, a mouse gene required for trophoblast development

Nat Genet. 1995 Mar;9(3):235-42. doi: 10.1038/ng0395-235.

Abstract

The mouse gene Mash2 encodes a transcription factor required for development of trophoblast progenitors. Mash2-homozygous mutant embryos die at 10 days postcoitum from placental failure. Here we show that Mash2 is genomically imprinted. First, Mash2+/- embryos inheriting a wild-type allele from their father die at the same stage as -/- embryos, with a similar placental phenotype. Second, the Mash2 paternal allele is initially expressed by groups of trophoblast cells at 6.5 and 7.5 days post-coitum, but appears almost completely repressed by 8.5 days post-coitum. Finally, we have genetically and physically mapped Mash2 to the distal region of chromosome 7, within a cluster of imprinted genes, including insulin-2, insulin-like growth factor-2 and H19.

Publication types

  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Alleles
  • Animals
  • Base Sequence
  • Basic Helix-Loop-Helix Transcription Factors
  • Chromosome Mapping
  • Crosses, Genetic
  • DNA Primers / genetics
  • DNA-Binding Proteins / genetics*
  • Female
  • Gene Expression Regulation, Developmental
  • Genetic Linkage
  • Genomic Imprinting*
  • Gestational Age
  • Heterozygote
  • Homozygote
  • Male
  • Mice
  • Molecular Sequence Data
  • Mutation
  • Pregnancy
  • Transcription Factors*
  • Trophoblasts / metabolism*

Substances

  • Ascl2 protein, mouse
  • Basic Helix-Loop-Helix Transcription Factors
  • DNA Primers
  • DNA-Binding Proteins
  • Transcription Factors