[Rothmund-Thomson syndrome with reduced DNA repair capacity]

Ann Dermatol Venereol. 1996;123(6-7):395-7.
[Article in French]

Abstract

Introduction: Rothmund-Thomson syndrome is a genodermatosis associated with early poikilodermal lesions. The condition usually occurs in children. Features include skeletal deformations and increased risk of malignancy.

Case report: A 3 and a half year-old girl with poikilodermal lesions predominating in photoexposed areas presented a rash after exposure to sun. The first manifestations occurred during the first months of life. Examination of DNA repair on a culture of UV irradiated fibroblasts showed reduced DNA repair capacity.

Discussion: Other childhood photodermatoses were eliminated by the clinical signs. It would be important to know whether there is a correlation between DNA repair and development of neoplasia in Rothmund-Thomson syndrome.

Publication types

  • Case Reports
  • English Abstract

MeSH terms

  • Child, Preschool
  • DNA Repair*
  • Female
  • Humans
  • Photosensitivity Disorders / etiology*
  • Rothmund-Thomson Syndrome / genetics*
  • Rothmund-Thomson Syndrome / pathology