[Neurosarcoma associated with neurofibromatosis 1. Apropos of a case and review of the literature]

Presse Med. 1997 Mar 29;26(10):458-63.
[Article in French]

Abstract

Background: Type 1 neurofibromatosis considerably increases the risk of cancer development, particularly neurosarcoma. We report a case in a patient with chemosensitive metastatic neurosarcoma.

Case report: A young female patient with familial type 1 neurofibromatosis developed pleural metastasis of a neurosarcoma located on the arm. This tumor was initially highly sensitive to chemotherapy, but relapse occurred.

Discussion: Follow-up in the order members of the family was particularly difficult to organize. One sister developed cerebral astrocytoma. Neurosarcomas develop earlier in patients with type 1 neurofibromatosis, worsening prognosis. We suggest a prospective and structured registration of such cases using a network of clinicians and pathologists in order to improve management schemes.

Publication types

  • Case Reports
  • English Abstract
  • Review

MeSH terms

  • Adult
  • Female
  • Humans
  • Neoplasms, Multiple Primary / pathology*
  • Neurofibromatosis 1 / genetics
  • Neurofibromatosis 1 / pathology*
  • Neurofibromatosis 1 / therapy
  • Neurofibrosarcoma / pathology*
  • Neurofibrosarcoma / secondary
  • Neurofibrosarcoma / therapy
  • Soft Tissue Neoplasms / pathology*