Three cases of platelet alloimmunisation associated with the presence of a novel platelet-specific antibody

Vox Sang. 1998;75(3):242-6.

Abstract

Background and objectives: In three cases of platelet alloimmunisation, a platelet-specific alloantibody was detected which could not be classified within the known human platelet alloantigen or HLA systems. The first case was of a family in which two siblings suffered neonatal alloimmune thrombocytopenia at birth. In the second case, the newborn was suffering from phocomelia with hypoplastic thrombocytopenia. The third case was a male who became refractory to transfusions of HLA-matched platelets after a related bone marrow transplantation.

Materials and methods: The serum samples were investigated by: enzyme-linked immunosorbent assay, platelet suspension immunofluorescence test (PSIFT), monoclonal antibody immobilisation of platelet antigens assay (MAIPA), and by the lymphocytotoxicity test.

Results: The antibody gave positive reactions with 26% of normal donor platelets. Surprisingly, no platelet-specific antibody was detected by PSIFT or by MAIPA and there was no evidence found to support classifying the antibody within the HLA system.

Conclusion: The reactivity pattern of the antibody detected and the clinical presentation of the three cases described, strongly suggest the presence of an additional platelet-specific alloantigen system.

Publication types

  • Case Reports

MeSH terms

  • Antigens, Human Platelet / immunology*
  • Blood Platelets / immunology*
  • Bone Marrow Transplantation / immunology
  • Ectromelia / complications
  • Enzyme-Linked Immunosorbent Assay
  • Female
  • Fluorescent Antibody Technique, Indirect
  • HLA Antigens / immunology
  • Humans
  • Immunity, Maternally-Acquired
  • Immunization*
  • Infant, Newborn
  • Integrin beta3
  • Isoantibodies / biosynthesis
  • Isoantibodies / immunology*
  • Male
  • Middle Aged
  • Pregnancy
  • Thrombocytopenia / complications
  • Thrombocytopenia / congenital*
  • Thrombocytopenia / immunology
  • Transplantation, Homologous / immunology

Substances

  • 2b alloantigen, human
  • Antigens, Human Platelet
  • HLA Antigens
  • ITGB3 protein, human
  • Integrin beta3
  • Isoantibodies
  • human platelet antigen 1b